Common molecular signature in SOD1 for both sporadic and familial amyotrophic lateral sclerosis.

نویسندگان

  • Arie Gruzman
  • William L Wood
  • Evgenia Alpert
  • M Dharma Prasad
  • Robert G Miller
  • Jeffery D Rothstein
  • Robert Bowser
  • Ronald Hamilton
  • Troy D Wood
  • Don W Cleveland
  • Vishwanath R Lingappa
  • Jian Liu
چکیده

Amyotrophic lateral sclerosis (ALS) is a devastating motor neuron degenerative disease whose etiology and pathogenesis remain poorly understood. Most cases of ALS ( approximately 90%) are sporadic (SALS), occurring in the absence of genetic associations. Approximately 20% of familial ALS (FALS) cases are due to known mutations in the copper, zinc superoxide dismutase (SOD1) gene. Molecular evidence for a common pathogenesis of SALS and FALS has remained elusive. Here we use covalent chemical modification to reveal an attribute of spinal cord SOD1 common to both SOD1-linked FALS and SALS, but not present in normal or disease-affected tissues from other neurodegenerative diseases, including Alzheimer's, Parkinson's, and Huntington's diseases and spinal muscular atrophy, a non-ALS motor neuron disease. Biotinylation reveals a 32-kDa, covalently cross-linked SOD1-containing protein species produced not only in FALS caused by SOD1 mutation, but also in SALS. These studies use chemical modification as a novel tool for the detection of a disease-associated biomarker. Our results identify a shared molecular event involving a known target gene and suggest a common step in the pathogenesis between SALS and FALS.

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عنوان ژورنال:
  • Proceedings of the National Academy of Sciences of the United States of America

دوره 104 30  شماره 

صفحات  -

تاریخ انتشار 2007